Rodgers S, and Pimentel J. Rare lymphatic malformation of external ear canal with history of sclerotherapy. American Journal of Dermatopathology 2021; 43(SUPPL 8):S12.
Am J Dermatopathol
An 8-year-old boy with history of conductive hearing loss, presented with a 3.1 x 3.1 x 2 cm left postauricular mass diagnosed as lymphatic malformation on imaging. Treatment with bleomycin sclerotherapy led to successful improvement of the malformation. Seven months post-treatment, he presented to his audiologist with several months of intermittent bleeding and pain from the ear. Upon examination by otolaryngology, a 0.5 cm papillary lesion was discovered in the external ear canal which had not been identified previously. A biopsy demonstrated a papillary proliferation of dilated thin walled lymphatic channels expanding multiple dermal papillae, consistent with lymphatic malformation. We propose that this lesion could represent extension of the original lesion or a new lesion secondary to regional lymphatic damage from prior sclerotherapy. Lymphatic malformation is rare within the external ear canal. Moreover, this case developed after treatment by regional sclerotherapy. To our knowledge, this sequela has not been previously documented in the literature but may be underreported. Therefore, routine regional follow up may be warranted in any periauricular sclerotherapy for lymphatic malformation.